Genetic disruption of mammalian endoplasmic reticulum‐associated protein degradation: Human phenotypes and animal and cellular disease models

S Badawi, FE Mohamed, DS Varghese, BR Ali - Traffic, 2023 - Wiley Online Library
Endoplasmic reticulum‐associated protein degradation (ERAD) is a stringent quality control
mechanism through which misfolded, unassembled and some native proteins are targeted …

Bridging clinical care and research in Ontario, Canada: Maximizing diagnoses from reanalysis of clinical exome sequencing data

T Hartley, É Soubry, M Acker, M Osmond… - Clinical …, 2023 - Wiley Online Library
We examined the utility of clinical and research processes in the reanalysis of publicly‐
funded clinical exome sequencing data in Ontario, Canada. In partnership with eight sites …

STIGMA: Single-cell tissue-specific gene prioritization using machine learning

S Balachandran, CA Prada-Medina, MA Mensah… - The American Journal of …, 2024 - cell.com
Clinical exome and genome sequencing have revolutionized the understanding of human
disease genetics. Yet many genes remain functionally uncharacterized, complicating the …

Exome sequencing links the SUMO protease SENP7 with fatal arthrogryposis multiplex congenita, early respiratory failure and neutropenia

N Samra, NS Jansen, I Morani, RR Kakun… - Journal of Medical …, 2023 - jmg.bmj.com
Background SUMOylation involves the attachment of small ubiquitin-like modifier (SUMO)
proteins to specific lysine residues on thousands of substrates with target-specific effects on …

A somatic UBA2 variant preceded ETV6-RUNX1 in the concordant BCP-ALL of monozygotic twins

B Bang, J Eisfeldt, G Barbany, A Harila-Saari… - Blood …, 2022 - ashpublications.org
Genetic analysis of leukemic clones in monozygotic twins with concordant acute
lymphoblastic leukemia (ALL) has proved a unique opportunity to gain insight into the …

Identifying phenotypic expansions for congenital diaphragmatic hernia plus (CDH+) using DECIPHER data

A Hardcastle, AM Berry, IM Campbell… - American Journal of …, 2022 - Wiley Online Library
Congenital diaphragmatic hernia (CDH) can occur in isolation or in conjunction with other
birth defects (CDH+). A molecular etiology can only be identified in a subset of CDH cases …

Variable clinical presentation of split hand/foot malformation syndrome in a family with microduplication of 10q24. 32: a case report

D Akimova, T Markova, M Ampleeva… - Frontiers in Genetics, 2024 - frontiersin.org
SHFM (Split Hand/Foot Malformation) is a heterogeneous group of disorders characterized
by the presence of clefts in the hands and feet, along with syndactyly of the digits. In this …

A novel frameshift variant in UBA2 causing split-hand/foot malformations in a Pakistani family

A Parveen, M Tariq, SA Khan, N Kakar, A Arif… - Human Genome …, 2023 - nature.com
Split-hand/foot malformation (SHFM) shows diverse heterogeneity and manifests with
reduced penetrance and variable expressivity. This study investigated the underlying …

Untersuchung des diagnostischen Potenzials der Ganzgenomsequenzierung am Beispiel von 69 Fällen mit angeborenen Extremitätenfehlbildungen

J Elsner - 2023 - refubium.fu-berlin.de
Seit der Sequenzierung des ersten menschlichen Genoms 2001 hat die Ganz-Genom-
Analyse (Whole-Genome-Sequencing, WGS) große Fortschritte gemacht. Mittlerweile ist es …

Atypical presentation of ACCES syndrome resembling dominant Spondyloepiphyseal dysplasia tarda

A Sezer, Z Özdemir, E Özkan… - American Journal of … - Wiley Online Library
Abstract Aplasia Cutis Congenita with Ectrodactyly Skeletal Syndrome (ACCES, OMIM#
619959) is an extremely rare multiple congenital anomalies syndrome caused by …