[HTML][HTML] Recombinant adeno-associated viral vectors (rAAV)-vector elements in ocular gene therapy clinical trials and transgene expression and bioactivity assays

TM Buck, J Wijnholds - International journal of molecular sciences, 2020 - mdpi.com
Inherited retinal dystrophies and optic neuropathies cause chronic disabling loss of visual
function. The development of recombinant adeno-associated viral vectors (rAAV) gene …

[HTML][HTML] AAV targeting of glial cell types in the central and peripheral nervous system and relevance to human gene therapy

SJ O'Carroll, WH Cook, D Young - Frontiers in Molecular …, 2021 - frontiersin.org
Different glial cell types are found throughout the central (CNS) and peripheral nervous
system (PNS), where they have important functions. These cell types are also involved in …

[HTML][HTML] Inherited retinal degenerations: current landscape and knowledge gaps

JL Duncan, EA Pierce, AM Laster… - … vision science & …, 2018 - tvst.arvojournals.org
Inherited retinal degenerations (IRDs) represent a diverse group of progressive, visually
debilitating diseases that can lead to blindness in which mutations in genes that are critical …

[PDF][PDF] AAV-mediated gene augmentation therapy of CRB1 patient-derived retinal organoids restores the histological and transcriptional retinal phenotype

N Boon, X Lu, CA Andriessen, I Moustakas, TM Buck… - Stem cell reports, 2023 - cell.com
Retinitis pigmentosa and Leber congenital amaurosis are inherited retinal dystrophies that
can be caused by mutations in the Crumbs homolog 1 (CRB1) gene. CRB1 is required for …

[HTML][HTML] Improving adeno-associated viral (AAV) vector-mediated transgene expression in retinal ganglion cells: comparison of five promoters

B Nieuwenhuis, E Laperrousaz, JR Tribble… - Gene Therapy, 2023 - nature.com
Recombinant adeno-associated viral vectors (AAVs) are an effective system for gene
transfer. AAV serotype 2 (AAV2) is commonly used to deliver transgenes to retinal ganglion …

[PDF][PDF] Human iPSC-derived retinas recapitulate the fetal CRB1 CRB2 complex formation and demonstrate that photoreceptors and Müller glia are targets of AAV5

PM Quinn, TM Buck, AA Mulder, C Ohonin, CH Alves… - Stem Cell Reports, 2019 - cell.com
Human retinal organoids from induced pluripotent stem cells (hiPSCs) can be used to
confirm the localization of proteins in retinal cell types and to test transduction and …

[HTML][HTML] Organoids and organ chips in ophthalmology

N Manafi, F Shokri, K Achberger, M Hirayama… - The Ocular Surface, 2021 - Elsevier
Recent advances have driven the development of stem cell-derived, self-organizing, three-
dimensional miniature organs, termed organoids, which mimic different eye tissues …

Genotypic and phenotypic characteristics of CRB1-associated retinal dystrophies: a long-term follow-up study

M Talib, MJ van Schooneveld, MM van Genderen… - Ophthalmology, 2017 - Elsevier
Purpose To describe the phenotype, long-term clinical course, clinical variability, and
genotype of patients with CRB1-associated retinal dystrophies. Design Retrospective cohort …

[HTML][HTML] CRB1-associated retinal dystrophies: genetics, clinical characteristics, and natural history

MD Varela, M Georgiou, Y Alswaiti, J Kabbani… - American Journal of …, 2023 - Elsevier
PURPOSE To analyze the clinical characteristics, natural history, and genetics of CRB1-
associated retinal dystrophies. DESIGN Multicenter international retrospective cohort study …

[HTML][HTML] Retinal dystrophies, genomic applications in diagnosis and prospects for therapy

BM Nash, DC Wright, JR Grigg, B Bennetts… - Translational …, 2015 - ncbi.nlm.nih.gov
Retinal dystrophies (RDs) are degenerative diseases of the retina which have marked
clinical and genetic heterogeneity. Common presentations among these disorders include …