CDG therapies: from bench to bedside

S Brasil, C Pascoal, R Francisco… - International journal of …, 2018 - mdpi.com
Congenital disorders of glycosylation (CDG) are a group of genetic disorders that affect
protein and lipid glycosylation and glycosylphosphatidylinositol synthesis. More than 100 …

GNE myopathy: from clinics and genetics to pathology and research strategies

O Pogoryelova, JA González Coraspe… - Orphanet journal of rare …, 2018 - Springer
GNE myopathy is an ultra-rare autosomal recessive disease, which starts as a distal muscle
weakness and ultimately leads to a wheelchair bound state. Molecular research and animal …

Altered behavioral performance and live imaging of circuit-specific neural deficiencies in a zebrafish model for psychomotor retardation

D Zada, A Tovin, T Lerer-Goldshtein, GD Vatine… - PLoS …, 2014 - journals.plos.org
The mechanisms and treatment of psychomotor retardation, which includes motor and
cognitive impairment, are indefinite. The Allan-Herndon-Dudley syndrome (AHDS) is an X …

In vivo and in vitro genome editing to explore GNE functions

N Ilouz, A Harazi, M Guttman, A Daya… - Frontiers in Genome …, 2022 - frontiersin.org
GNE myopathy is an adult onset neuromuscular disorder characterized by slowly
progressive distal and proximal muscle weakness, caused by missense recessive mutations …

Generation and characterization of a novel gne Knockout Model in Zebrafish

H Livne, T Avital, S Ruppo, A Harazi… - Frontiers in Cell and …, 2022 - frontiersin.org
GNE Myopathy is a rare, recessively inherited neuromuscular worldwide disorder, caused
by a spectrum of bi-allelic mutations in the human GNE gene. GNE encodes a bi-functional …

Genetic defects in the hexosamine and sialic acid biosynthesis pathway

AP Willems, BGM van Engelen, DJ Lefeber - Biochimica et Biophysica Acta …, 2016 - Elsevier
Background Congenital disorders of glycosylation are caused by defects in the glycosylation
of proteins and lipids. Classically, gene defects with multisystem disease have been …

Role of HSP70 chaperone in protein aggregate phenomenon of GNE mutant cells: Therapeutic lead for GNE Myopathy

R Yadav, SS Devi, J Oswalia, S Ramalingam… - The International Journal …, 2022 - Elsevier
Limited treatment options and research in understanding the pathomechanisms of rare
diseases has raised concerns about their therapeutic development. One such poorly …

“Muscling” throughout life: integrating studies of muscle development, homeostasis, and disease in zebrafish

MF Goody, EV Carter, EA Kilroy, L Maves… - Current topics in …, 2017 - Elsevier
The proper development and function of skeletal muscle is vital for health throughout the
lifespan. Skeletal muscle function enables posture, breathing, and locomotion; and also …

Induced sterility in fish and its potential and challenges for aquaculture and germ cell transplantation technology: a review

A Golpour, MAM Siddique, DH Siqueira-Silva… - Biologia, 2016 - degruyter.com
Interest in reproductively sterile fish in aquaculture has prompted research into their
production. Several methods are available for inducing sterility and optimizing its application …

Functional characterization of GNE mutations prevalent in Asian subjects with GNE myopathy, an ultra-rare neuromuscular disorder

S Sharma, P Chanana, R Bharadwaj, S Bhattacharya… - Biochimie, 2022 - Elsevier
Abstract UDP-GlcNAc 2-epimerase/ManNAc kinase (GNE) is a bifunctional enzyme (N-
terminal epimerase and C-terminal Kinase domain) that catalyses the rate limiting step in …