How zebrafish can drive the future of genetic-based hearing and balance research

L Sheets, M Holmgren, KS Kindt - Journal of the Association for Research …, 2021 - Springer
Over the last several decades, studies in humans and animal models have successfully
identified numerous molecules required for hearing and balance. Many of these studies …

Detecting novel ototoxins and potentiation of ototoxicity by disease settings

AB Coffin, R Boney, J Hill, C Tian, PS Steyger - Frontiers in neurology, 2021 - frontiersin.org
Over 100 drugs and chemicals are associated with permanent hearing loss, tinnitus, and
vestibular deficits, collectively known as ototoxicity. The ototoxic potential of drugs is rarely …

Tiltable objective microscope visualizes selectivity for head motion direction and dynamics in zebrafish vestibular system

M Tanimoto, I Watakabe, S Higashijima - Nature communications, 2022 - nature.com
Spatio-temporal information about head orientation and movement is fundamental to the
sense of balance and motion. Hair cells (HCs) in otolith organs of the vestibular system …

Structural relationship between the putative hair cell mechanotransduction channel TMC1 and TMEM16 proteins

A Ballesteros, C Fenollar-Ferrer, KJ Swartz - Elife, 2018 - elifesciences.org
The hair cell mechanotransduction (MET) channel complex is essential for hearing, yet it's
molecular identity and structure remain elusive. The transmembrane channel–like 1 (TMC1) …

EMX2-GPR156-Gαi reverses hair cell orientation in mechanosensory epithelia

KS Kindt, A Akturk, A Jarysta, M Day, A Beirl… - Nature …, 2021 - nature.com
Hair cells detect sound, head position or water movements when their mechanosensory hair
bundle is deflected. Each hair bundle has an asymmetric architecture that restricts stimulus …

Retrograde mitochondrial transport is essential for organelle distribution and health in zebrafish neurons

A Mandal, HTC Wong, K Pinter… - Journal of …, 2021 - Soc Neuroscience
In neurons, mitochondria are transported by molecular motors throughout the cell to form
and maintain functional neural connections. These organelles have many critical functions …

Synaptic mitochondria regulate hair-cell synapse size and function

HC Wong, Q Zhang, AJ Beirl, RS Petralia, YX Wang… - Elife, 2019 - elifesciences.org
Sensory hair cells in the ear utilize specialized ribbon synapses. These synapses are
defined by electron-dense presynaptic structures called ribbons, composed primarily of the …

Lateral line ablation by ototoxic compounds results in distinct rheotaxis profiles in larval zebrafish

KC Newton, D Kacev, SRO Nilsson, AL Saettele… - Communications …, 2023 - nature.com
The zebrafish lateral line is an established model for hair cell organ damage, yet few studies
link mechanistic disruptions to changes in biologically relevant behavior. We used larval …

Distinct progenitor populations mediate regeneration in the zebrafish lateral line

ED Thomas, DW Raible - Elife, 2019 - elifesciences.org
Mechanosensory hair cells of the zebrafish lateral line regenerate rapidly following damage.
These renewed hair cells arise from the proliferation of surrounding support cells, which …

Complexes of vertebrate TMC1/2 and CIB2/3 proteins form hair-cell mechanotransduction cation channels

APJ Giese, WH Weng, KS Kindt, HHV Chang… - eLife, 2025 - elifesciences.org
Calcium and integrin-binding protein 2 (CIB2) and CIB3 bind to transmembrane channel-like
1 (TMC1) and TMC2, the pore-forming subunits of the inner-ear mechano-electrical …