Deep learning of the retina enables phenome-and genome-wide analyses of the microvasculature

SM Zekavat, VK Raghu, M Trinder, Y Ye, S Koyama… - Circulation, 2022 - Am Heart Assoc
Background: The microvasculature, the smallest blood vessels in the body, has key roles in
maintenance of organ health and tumorigenesis. The retinal fundus is a window for human …

The genetic architecture of primary biliary cholangitis

A Gerussi, M Carbone, C Corpechot… - European Journal of …, 2021 - Elsevier
Primary biliary cholangitis (PBC) is a rare autoimmune disease of the liver affecting the small
bile ducts. From a genetic point of view, PBC is a complex trait and several genetic and …

[HTML][HTML] A multi-layer functional genomic analysis to understand noncoding genetic variation in lipids

S Ramdas, J Judd, SE Graham, S Kanoni… - The American Journal of …, 2022 - cell.com
A major challenge of genome-wide association studies (GWASs) is to translate phenotypic
associations into biological insights. Here, we integrate a large GWAS on blood lipids …

Whole-exome sequencing reveals a role of HTRA1 and EGFL8 in brain white matter hyperintensities

R Malik, N Beaufort, S Frerich, B Gesierich… - Brain, 2021 - academic.oup.com
White matter hyperintensities (WMH) are among the most common radiological
abnormalities in the ageing population and an established risk factor for stroke and …

Systematic single-variant and gene-based association testing of thousands of phenotypes in 426,370 UK Biobank exomes

KJ Karczewski, M Solomonson, KR Chao, JK Goodrich… - Medrxiv, 2021 - medrxiv.org
Genome-wide association studies have successfully discovered thousands of common
variants associated with human diseases and traits, but the landscape of rare variation in …

[HTML][HTML] A novel quality-control procedure to improve the accuracy of rare variant calling in SNP arrays

TH Sun, YHJ Shao, CL Mao, MN Hung, YY Lo… - Frontiers in …, 2021 - frontiersin.org
Background: Single-nucleotide polymorphism (SNP) arrays are an ideal technology for
genotyping genetic variants in mass screening. However, using SNP arrays to detect rare …

[HTML][HTML] Clinical case study meets population cohort: identification of a BRCA1 pathogenic founder variant in Orcadians

SM Kerr, E Cowan, L Klaric, C Bell… - European Journal of …, 2023 - nature.com
We multiply ascertained the BRCA1 pathogenic missense variant c. 5207T> C; p.
Val1736Ala (V1736A) in clinical investigation of breast and ovarian cancer families from …

Assessing the contribution of rare-to-common protein-coding variants to circulating metabolic biomarker levels via 412,394 UK Biobank exome sequences

A Nag, L Middleton, RS Dhindsa, D Vitsios, E Wigmore… - MedRxiv, 2021 - medrxiv.org
Genome-wide association studies have established the contribution of common and low
frequency variants to metabolic biomarkers in the UK Biobank (UKB); however, the role of …

Rare Missense Functional Variants at COL4A1 and COL4A2 in Sporadic Intracerebral Hemorrhage

J Chung, G Hamilton, M Kim, S Marini, B Montgomery… - Neurology, 2021 - AAN Enterprises
Objective To test the genetic contribution of rare missense variants in COL4A1 and COL4A2
in which common variants are genetically associated with sporadic intracerebral …

Empowering rare variant burden-based gene-trait association studies via optimized computational predictor choice

D Kuang, R Li, Y Wu, J Weile, RA Hegele, FP Roth - bioRxiv, 2021 - biorxiv.org
Background Causal gene/trait relationships can be identified via observation of an excess
(or reduced) burden of rare variation in a given gene within humans who have that trait …